Cardiac Inflammatory Pseudotumor Following Atrial Septal Defect Repair: A Rare Complication Managed with Sirolimus and Bevacizumab

AuthorMersad Mehrnahaden
AuthorHamidreza Pouraliakbaren
AuthorAli Mohammadzadehen
AuthorMansoor Namazien
OrcidMersad Mehrnahad [0000-0002-8744-9219]en
OrcidHamidreza Pouraliakbar [0000-0002-2557-4030]en
OrcidAli Mohammadzadeh [0000-0002-3168-2599]en
OrcidMansoor Namazi [0000-0001-6188-9200]en
Issued Date2025-07-30en
AbstractIntroduction: Inflammatory pseudotumors (IPTs) of the heart are rare, non-neoplastic lesions that can mimic heart neoplasms and are exceptionally uncommon following congenital heart surgery. We report a unique case of a cardiac IPT presenting decades after atrial septal defect (ASD) repair, managed with surgical debulking and targeted therapy. Case Presentation: A 35-year-old woman with a history of ASD repair at age 6 presented in March 2023 with progressive exertional dyspnea over 5 months. Imaging revealed a 4.2 × 3.8 cm mass involving the interatrial septum (IAS), right atrium (RA), and superior vena cava (SVC). Debulking surgery in August 2023 confirmed an IPT histopathologically. Due to residual disease, she received sirolimus and bevacizumab, resulting in a reduction of the residual mass (2.1 × 1.8 cm) and complete resolution of symptoms by August 2024. Conclusions: This case demonstrates the first successful use of sirolimus-bevacizumab combination therapy for a cardiac IPT following ASD repair. This strategy offers a viable alternative for unresectable lesions and underscores the need for long-term surveillance in patients with prior cardiac surgery to detect rare inflammatory complications.en
DOIhttps://doi.org/10.5812/iranjradiol-162301en
URIhttps://brieflands.com/journals/ijradiology/articles/162301en
KeywordHeart Neoplasmsen
KeywordInflammatory Pseudotumoren
KeywordAtrial Septal Defecten
KeywordSirolimusen
KeywordBevacizumaben
KeywordMagnetic Resonance Imagingen
PublisherBrieflandsen
TitleCardiac Inflammatory Pseudotumor Following Atrial Septal Defect Repair: A Rare Complication Managed with Sirolimus and Bevacizumaben
TypeCase Reporten

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